International Surgery Journal | August 2022 | Vol 9 | Issue 8 Page 1
International Surgery Journal
Sharma R et al. Int Surg J. 2022 Aug;9(8):xxx-xxx
http://www.ijsurgery.com
pISSN 2349-3305 | eISSN 2349-2902
Case Series
Modified cone procedure along with bidirectional cavopulmonary
shunt for Ebstein anomaly in adult patients
Rakesh Sharma*, Satyajit Samal, Rahul Banik, Saket Aggarwal,
Sayyed Ehtesham Hussain Naqvi, Mohammed Abid Geelani
INTRODUCTION
Ebstein anomaly is a rare congenital malformation
affecting the tricuspid valve and right ventricle and
accounts for less than 1% of all congenital heart
diseases.
1
Wilhelm Ebstein, a German pathologist, first
described this anomaly in 1866.
2
Asymptomatic patients
with stable hemodynamic pass on to adulthood and are
diagnosed later as disease progresses and require surgical
treatment. After many unsuccessful attempts at repair, da
Silva described the cone reconstruction technique.
3,4
Modifications of this technique have been used by
Dearani and others and it has become the preferred repair
method for patients with Ebstein anomaly.
5-9
Here we
described the surgical technique and the results of
modified cone reconstruction along with bidirectional
Glenn shunt used for the treatment of Ebstein anomaly in
5 adult patients at a tertiary care referral centre in North
India.
CASE SERIES
All adult patients aged more than 18 years referred to us
with Ebstein anomaly from 2019 to 2021 were included
in the study. A total of 5 patients, all females underwent
the corrective surgery after a detailed clinical
examination, laboratory and echocardiographic
evaluation. They presented with symptoms of dyspnoea
ABSTRACT
Ebstein anomaly is an uncommon congenital cardiac disease affecting the tricuspid valve and right ventricle. Da silva
pioneered the cone reconstruction of tricuspid valve for surgical repair of this anomaly in 2007. We describe our
experience of 5 adult patients who underwent cone repair along with a bidirectional cavopulmonary shunt and
tricuspid annuloplasty ring placement at our institute. Five adult patients with Ebstein anomaly with progressive
disease and symptoms were taken up cone reconstruction from 2019 to 2021. Along with cone reconstruction of
tricuspid valve, we routinely added an end to side superior vena cava to right pulmonary artery shunt and a tricuspid
annuloplasty ring in the newly formed tricuspid annulus in all cases. All patients tolerated the procedure well and
easily weaned off cardiopulmonary bypass. There were no complications regarding bidirectional cavopulmonary
shunt and only one patient had a temporary heart block which was managed conservatively. This series shows routine
addition of a cavopulmonary shunt and an annuloplasty ring improves outcomes and can be performed at other
experienced cardiac surgery centres.
Keywords: Ebstein anomaly, Adult congenital heart disease, Modified cone reconstruction, Bidirectional
cavopulmonary shunt, Tricuspid annuloplasty ring
Department of Cardiothoracic Surgery, G. B. Pant Institute of Postgraduate Medical Education and Research
(GIPMER), New Delhi, India
Received: 20 June 2022
Revised: 02 July 2022
Accepted: 05 July 2022
*Correspondence:
Dr. Rakesh Sharma,
E-mail: raksy_222@yahoo.co.in
Copyright: © the author(s), publisher and licensee Medip Academy. This is an open-access article distributed under
the terms of the Creative Commons Attribution Non-Commercial License, which permits unrestricted non-commercial
use, distribution, and reproduction in any medium, provided the original work is properly cited.
DOI: https://dx.doi.org/10.18203/2349-2902.isj20221825