Volume 5 • Issue 2 • 1000216
J Cytol Histol
ISSN: 2157-7099 JCH, an open access journal
Research Article Open Access
Cooper and O’Toole, J Cytol Histol 2014, 5:2
DOI: 10.4172/2157-7099.1000216
Review Article Open Access
Detecting ALK Gene Rearrangements in Lung Cancer Cytology Specimens
Cooper WA
1-3
and O’Toole SA
1,2,4
1
Tissue Pathology and Diagnostic Oncology, Royal Prince Alfred Hospital, Camperdown, NSW, Australia
2
Sydney Medical School, University of Sydney, NSW, Australia
3
School of Medicine, University of Western Sydney, NSW, Australia
4
The Kinghorn Cancer Centre, Garvan Institute of Medical Research, Darlinghurst, NSW, Australia
*Corresponding author: Wendy Cooper, Department of Tissue Pathology and
Diagnostic Oncology, Royal Prince Alfred Hospital, Missenden Rd, Camperdown
NSW 2050, Australia, Tel: (+612) 9515 7804; Fax: (+612) 9515 8405; E-mail:
Wendy.Cooper@sswahs.nsw.gov.au
Received January 23, 2014; Accepted February 04, 2014; Published February
06, 2014
Citation: Cooper WA, O’Toole SA (2014) Detecting ALK Gene Rearrangements
in Lung Cancer Cytology Specimens. J Cytol Histol 5: 216. doi:10.4172/2157-
7099.1000216
Copyright: © 2014 Cooper WA, et al. This is an open-access article distributed
under the terms of the Creative Commons Attribution License, which permits
unrestricted use, distribution, and reproduction in any medium, provided the
original author and source are credited.
Abstract
Molecular testing for EGFR mutations and ALK gene rearrangements has become a routine part of lung cancer
pathological diagnosis, and is critical to determine the most effective therapies for patients with this poor prognosis
cancer. ALK gene rearrangements are seen particularly in adenocarcinoma of the lung and are associated with
an excellent response rate to targeted inhibition with crizotinib in clinical trials for many patients whose tumours
harbour this change. ALK gene rearrangement is generally observed at low incidence posing challenges for routine
detection. Since a high proportion of lung cancers are inoperable at presentation, cytology plays a central role in
diagnosis and provision of material for ALK testing. The advantages offered by cytology specimens for ALK and
other molecular testing are becoming increasingly recognised - cytology specimens tend to have a lower proportion
of contaminating stromal and other non-neoplastic cells and often have higher quality DNA than routine histology
specimens. One challenge is the often limited amount of cytological material obtaining in many lung cancer cytology
specimens. FISH testing for ALK gene rearrangement using a break-apart probe is the gold standard for testing
although there is a strong role for immunohistochemistry in ALK testing. This review highlights key aspects of ALK
testing in cytology specimens.
Keywords: Lung adenocarcinoma; ALK, Anaplastic lymphoma
kinase; FISH; Immunohistochemistry
Abbreviations: ALK: Anaplastic Lymphoma Kinase; EML4:
Echinoderm Microtubule Associated Protein-like 4; FISH: Fluorescent
in situ Hybridization; IHC: Immunohistochemistry; NSCLC: Non-
Small Cell Lung Carcinoma; NOS: Not Otherwise Specifed; RT-PCR:
Reverse-Transcriptase Polymerase Chain Reaction; TKI: Tyrosine
Kinase Inhibitor
Introduction
Accurate subtyping of non-small cell lung carcinoma (NSCLC)
is important due to implications for treatment selection and due to
the unique mutational profle of diferent lung cancer subtypes [1].
Adenocarcinomas, tumours with an adenocarcinoma component or
NSCLC- not otherwise specifed (NOS) (in cytology or small biopsy
samples) may harbour driver mutations amenable to targeted therapy
[2]. It is estimated that about 70% of patients with NSCLC present
with advanced stage disease not amenable to surgical resection, so
only diagnostic cytology or small biopsy tumour samples are available
for molecular analysis. Tere is evidence that cytology and small
biopsy specimens have equivalent capacity to accurately subtype
NSCLC [3]. Use of immunohistochemistry has become routine
for distinction of NSCLC subtypes in cytology (and small biopsy)
samples where morphology alone is insufcient [2] and in one study
immunohistochemistry was less frequently required in cytology
compared to small biopsy samples [3].
ALK Rearrangements in Lung Cancer
Identifcation of driver mutations has become essential in lung
cancer for selection of patients likely to respond to targeted therapies.
A small proportion of lung adenocarcinomas harbour activating ALK
(anaplastic lymphoma kinase) gene rearrangements and these tumours
are highly responsive to targeted tyrosine kinase inhibitors (TKIs) such
as crizotinib [4].
Te ALK gene is located on the short arm of chromosome 2 and
encodes a receptor tyrosine kinase that belongs to the insulin receptor
family [5]. Activation of ALK most commonly results from a small
chromosomal inversion (with or without a small deletion) resulting
in fusion of the intracellular kinase domain of ALK with the amino
terminal end of echinoderm microtubule associated protein-like 4 (EML4)
[6-8]. Diferent variants of EML4-ALK result from difering lengths of
the EML4 gene being incorporated into the fusion gene [6,9,10]. More
rarely, diferent partner genes fuse with ALK including KIF5B (kinesin
family member 5b), TFG (TRK-fused gene) and KLC-1(kinesin light
chain1) [11,12].Te various ALK fusion genes encode a constitutively
activated tyrosine kinase [7,11] that stimulates cell proliferation,
survival and migration mediated through RAS/RAF/MAPK1, PI3K/
AKT and JAK3-STAT3 signalling pathways [10,13]. Mouse models
expressing EML4-ALK develop multiple lung adenocarcinomas that
are susceptible to pharmacologic ALK inhibition [14].
Studies from unselected Western populations mostly report
ALK rearrangements in about 4% of NSCLC [5]. We found ALK
rearrangements in 1% of lung adenocarcinomas in an Australian
multicenter study [15]. Te clinicopathological features associated with
ALK rearrangements are similar to the profle associated with EGFR
mutations. ALK rearrangements are associated with younger patient
age and never-smokers or light smokers [6,15-19], however, racial and
gender associations are less pronounced for ALK.
In NSCLC, ALK rearrangements occur almost exclusively in
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ISSN: 2157-7099