Acta Neurol Scand. 2017;1–8. wileyonlinelibrary.com/journal/ane
|
1 © 2017 John Wiley & Sons A/S.
Published by John Wiley & Sons Ltd
Accepted: 16 December 2016
DOI: 10.1111/ane.12749
ORIGINAL ARTICLE
Narcolepsy patients’ blood-based miRNA expression profiling:
miRNA expression differences with Pandemrix vaccination
N. Mosakhani
1
| V. Sarhadi
1
| P. Panula
2
| M. Partinen
3,4
| S. Knuutila
1
1
Department of Pathology, University of
Helsinki, Helsinki, Finland
2
Neuroscience Center, Biomedicum, University
of Helsinki, Helsinki, Finland
3
Department of Clinical Neurosciences,
University of Helsinki, Helsinki, Finland
4
Helsinki Sleep Clinic, Vitalmed Research
Center, Helsinki, Finland
Correspondence
S. Knuutila, Department of Pathology,
University of Helsinki, Helsinki, Finland.
Email: sakari.knuutila@helsinki.fi
Funding information
Academic of Finland; the Suomen
Lääketieteen Fundation; Sigrid Jusélius
Foundation; the Finnish Cancer Organizations
Objectives: Narcolepsy is a neurological sleep disorder characterized by excessive
daytime sleepiness and nighttime sleep disturbance. Among children and adolescents
vaccinated with Pandemrix vaccine in Finland and Sweden, the number of narcolepsy
cases increased. Our aim was to identify miRNAs involved in narcolepsy and their as-
sociation with Pandemrix vaccination.
Materials and methods: We performed global miRNA proofing by miRNA microarrays
followed by RT-PCR verification on 20 narcolepsy patients (Pandemrix-associated and
Pandemrix-non-associated) and 17 controls (vaccinated and non-vaccinated).
Results: Between all narcolepsy patients and controls, 11 miRNAs were differentially
expressed; 17 miRNAs showed significantly differential expression between
Pandemrix-non-associated narcolepsy patients and non-vaccinated healthy controls.
MiR-188-5p and miR-4499 were over-expressed in narcolepsy patients vs healthy
controls. Two miRNAs, miR-1470 and miR-4455, were under-expressed in Pandemrix-
associated narcolepsy patients vs Pandemrix-non-associated narcolepsy patients.
Conclusions: We identified miRNA expression patterns in narcolepsy patients that
linked them to mRNA targets known to be involved in brain-related pathways or brain
disorders.
KEYWORDS
miRNA, narcolepsy, Pandemrix vaccine
1 | INTRODUCTION
Narcolepsy is a chronic neurological sleep disorder and neurodegen-
erative disease. These patients are characterized by excessive daytime
sleepiness (EDS) and cataplexy (a sudden weakening of posture mus-
cle tone usually triggered by emotion) caused by the lack of orexin
neurons in the lateral hypothalamus. Narcolepsy affects approxi-
mately 0.02% of the population worldwide.
1
In Finland, narcolepsy-
cataplexy prevalence among adults according to one 1994 report was
26/100 000.
2
Possible environmental risk factors for narcolepsy in-
clude streptococcal infection and viral infections including influenza.
3
In 2009, there occurred a pandemic of influenza A (H1N1 subtype),
and in August 2010, alerts in Finland and Sweden
4, 5
warned of a
sudden and marked increase in new cases of narcolepsy in children
and adolescents who had been vaccinated against the H1N1 influenza
virus with Pandemrix vaccine.
MicroRNAs (miRs) are non-coding, single-stranded regulatory
RNA molecules, 18-25 nucleotides in length, involved in the post-
transcriptional regulation of gene expression. They play important
roles in the development and maintenance of diverse cellular pro-
cesses including proliferation, differentiation, motility, and apopto-
sis.
6
Dysfunctions of miRNAs are associated with a broad spectrum
of diseases. MiRNAs are potential regulators of drug efficacy,
7
and
they offer possible applications in molecular diagnosis and in molec-
ular prognosis.
8
Their roles have been identified in neuronal processes, brain
morphogenesis, neuronal cell differentiation, and transcription of
neuronal-specific genes.
9
They occur at stable functional levels in all
biological circulating fluids such as plasma, urine, tears, saliva, and CSF,
which makes them promising candidates as biomarkers.
10, 11
Changes
in miRNA levels occur in plasma, peripheral blood mononuclear cells,
and CSF from patients with neurodegenerative diseases.
12-14