www.thelancet.com/child-adolescent Vol 2 December 2018 855
Articles
Lancet Child Adolesc Health
2018; 2: 855–62
Published Online
October 15, 2018
http://dx.doi.org/10.1016/
S2352-4642(18)30293-1
See Comment page 840
*Collaborators are listed at the
end of this paper
Department of Cardiology
(K Miyata MD, M Miura MD),
Clinical Research Support
Center (T Kaneko MS,
Y Morikawa MD),
and Department of General
Pediatrics (H Sakakibara MD,
T Matsushima MD), Tokyo
Metropolitan Children’s
Medical Center, Tokyo, Japan;
Department of Pediatrics,
Tokyo Metropolitan Bokutoh
Hospital, Tokyo, Japan
(M Misawa MD); Department of
Pediatrics, Saiseikai
Utsunomiya Hospital, Tochigi,
Japan (T Takahashi MD);
Department of Pediatrics,
National Hospital Organization
Saitama National Hospital,
Saitama, Japan
(M Nakazawa MD); Department
of Pediatrics, Saitama City
Hospital, Saitama, Japan
(T Tamame MD); Department of
Pediatrics, Kawasaki Municipal
Hospital, Kanagawa, Japan
(T Tsuchihashi MD);
Department of Pediatrics,
Yokohama Municipal Citizen’s
Hospital, Kanagawa, Japan
(Y Yamashita MD); Department
of Pediatrics, Tama-Hokubu
Medical Center, Tokyo, Japan
(T Obonai MD); Department of
Pediatrics, Tokyo Metropolitan
Ohtsuka Hospital, Tokyo, Japan
(M Chiga MD); Department of
Pediatrics, Ota Memorial
Hospital, Gunma, Japan
(N Hori MD); Department of
Pediatrics, National Hospital
Organization Tokyo Medical
Center, Tokyo, Japan
(O Komiyama MD);
and Department of Pediatrics,
Keio University School of
Efficacy and safety of intravenous immunoglobulin plus
prednisolone therapy in patients with Kawasaki disease
(Post RAISE): a multicentre, prospective cohort study
Koichi Miyata, Tetsuji Kaneko, Yoshihiko Morikawa, Hiroshi Sakakibara, Takahiro Matsushima, Masahiro Misawa, Tsutomu Takahashi,
Maki Nakazawa, Takuya Tamame, Takatoshi Tsuchihashi, Yukio Yamashita, Toshimasa Obonai, Michiko Chiga, Naoaki Hori, Osamu Komiyama,
Hiroyuki Yamagishi, Masaru Miura, on behalf of the Post RAISE group*
Summary
Background The RAISE study showed that additional prednisolone improved coronary artery outcomes in patients
with Kawasaki disease at high risk of intravenous immunoglobulin (IVIG) resistance. However, no studies have been
done to test the steroid regimen used in the RAISE study. We therefore aimed to verify the efcacy and safety of
primary IVIG plus prednisolone.
Methods We did a multicentre, prospective cohort study at 34 hospitals in Japan. We included patients diagnosed with
Kawasaki disease according to the Japanese diagnostic criteria, and excluded those who were treated at other hospitals
before being transferred to a participating hospital. Patients who were febrile at diagnosis received primary IVIG
(2 g/kg per 24 h) and oral aspirin (30 mg/kg per day) until the fever resolved, followed by oral aspirin (5 mg/kg per day)
for 2 months after Kawasaki disease onset. We stratifed patients using the Kobayashi score into predicted IVIG non-
responders (Kobayashi score ≥5) or predicted IVIG responders (Kobayashi score <5). For predicted non-responders,
each hospital independently decided whether to add prednisolone (intravenous injection of 2 mg/kg per day for 5 days)
to the primary IVIG treatment, according to their respective treatment policy, and we further divided these patients
based on the primary treatment received. The primary endpoint was the incidence of coronary artery abnormalities
determined by two-dimensional echocardiography at 1 month after the primary treatment in predicted non-responders
treated with primary IVIG plus prednisolone. Coronary artery abnormalities were defned according to the criteria of
the Japanese Ministry of Health and Welfare and of the American Heart Association (AHA). This study is registered
with the University Hospital Medical Information Network Clinical Trials Registry, number UMIN000007133.
Findings From July 1, 2012, to June 30, 2015, we enrolled 2628 patients with Kawasaki disease, of whom
724 (27∙6%) were predicted IVIG non-responders who received IVIG plus prednisolone as primary treatment.
132 (18·2%) of 724 patients did not respond to primary treatment. Among patients with complete data, coronary
artery abnormalities were present in 40 (incidence rate 5·9%, 95% CI 4·3–8·0) of 676 patients according to the AHA
criteria or in 26 (3·8%, 2·5–5·6) of 677 patients according to the Japanese criteria. Serious adverse events were
reported in 12 (1·7%) of 724 patients treated with primary IVIG plus prednisolone; two of these patients had
hypertension and bacteraemia that was probably related to prednisolone. One patient died possibly due to severe
infammation from the Kawasaki disease itself.
Interpretation Primary IVIG plus prednisolone therapy in this study had an efect similar to that seen in the RAISE
study in reducing the non-response rate and decreasing the incidence of coronary artery abnormalities. A primary
IVIG and prednisolone combination therapy might prevent coronary artery abnormalities and contribute to lowering
medical costs.
Funding Tokyo Metropolitan Government Hospitals and the Japan Kawasaki Disease Research Center.
Copyright © 2018 Elsevier Ltd. All rights reserved.
Introduction
Kawasaki disease is an acute, autoinfammatory systemic
vasculitis of unknown cause that leads to the formation of
coronary artery abnormalities. Intravenous immuno-
globulin (IVIG) and oral aspirin are the standard therapy
for Kawasaki disease, but approximately 15–20% of
patients do not respond to such treatment
1–3
and are at
risk for coronary artery abnormalities even if they receive
several rescue treatments.
The indications for corticosteroid therapy in patients
with Kawasaki disease are controversial. All studies that
showed an increase in incidence of coronary artery
abnormalities due to corticosteroids
4,5
were retrospectively
done; therefore, these studies were unable to eliminate
confounders by indication because these patients
typically had increased disease severity. In several
randomised controlled studies, primary IVIG combined
with a corticosteroid decreased the incidence of coronary