Original Contributions
Sensorineural Hearing Loss Among Sickle Cell
Disease Patients From Southern Brazil
Otavio Piltcher, MD, MSc, Luciana Cigana, Joao Friedriech, MD,
Fernando de Andrade Quintanilha Ribeiro, MD, PhD, and
Sady Selaimen da Costa, MD, MSc, PhD
Purpose: A case-control study was done to confirm the higher prevalence of sensorineural
hearing loss (SNHL) among sickle cell patients (HbSS) from southern Brazil.
Patients and Methods- Twenty-eight patients and 28 matched normal controls were studied.
Besides complete anamneses and physical otolaryngological examination, all individuals had
audiometric and tympanometric testings to determine the presence of SNHL or middle ear
problems. The only significant difference between groups was the presence of a positive
history of otologic symptoms (hearing loss, dizziness or tinnitus) and neurological sequelae in
the HbSS patients.
Results: Six patients (21.4%) presented with SNHL compared with one control (3.6%)
(Fisher's one-tailed P = .05; OR, 7.36 (95% CI, 0.82, 65.83). The average age of HbSS
diagnosis was higher among the patients with SNHL (10 years _+ 8.3) than those without
SNHL (5.43 years _+ 5.65), but this was not significant (analysis of variance P > .05). More
patients 25 years and older on the examination date had SNHL than younger patients
(Fisher's 2-tailed P < .05). Sixty-seven percent of the patients with SNHL had alterations in
the acoustic reflex, and a surprising 27% of the patients without NSHL also presented with
some elevation or an absence of acoustic reflex.
Conclusions: These data indicate that patients with HbSS from southern Brazil are more
predisposed to the development of sensorineural hearing problems than the general
population.
(Am J Otolaryngol 2000;21:75-79. Copyright © 2000 by W.B. Saunders Company)
Sickle cell disease (SCD) was first described
by Herrick in 1910. A chronic hemolytic ane-
mia and vaso-occlusive events that lead to a
variety of signs and symptoms characterize
the disease. It is caused by a single-point
mutation in the 6th position of the hemoglo-
bin's beta chain. The negative amino-acid glu-
tamic acid is replaced by valine, a hydropho-
bic amino acid. This substitution affects the
physicochemical properties of the red blood
From the Hospital de Clinicas de Porto Alegre; and the
Faculdade de Ci6ncias M~dicas da Santa Casa de Sao
Paulo, Brazil.
Supported in part by Funda£Ao de Amparo a Pesquisa
do Rio Grande do Sul (FAPERGS)--grant 96/60433.5.
Address reprint requests to Otavio Piltcher, MD, MSc,
Rua Miguel Tostes 533--201/202, Porto Alegre--RGS--
Brazil 90430-061.
Copyright © 2000 by W.B. Saunders Company
0196-0709/00/2102-0001 $10.00/0
cell, causing morphological modifications that
resemble a sickle shape. Affected red blood
cells have a shorter life span and may cause
microvascular occlusions. Indeed, all signs
and symptoms of the disease are directly or
indirectly correlated with these alterations.
The prevalence of SCD is high among Afri-
cans and their descendents, Arabs, Central
and South Americans, and people of the Medi-
terranean area. 1-3 In Brazil, SCD is the most
common heredity disease, affecting from 0.1%
to 0.3% of the black population and a rising
number of whites. Approximately one of every
1,000 to 1,500 live Brazilian births is affected
by or is a carrier of the SCD allele. 4 In 1983, the
life expectancy of affected homozygotic indi-
viduals in Brazil was reported to be 16 years,
with a range of from 4 to 28 years. 5 More
recently, a rising life expectancy has been
American Journal of Otolaryngology,Vo121, No 2 (March-April), 2000: pp 75-79 75