0041-1337/03/7905-1482/0
TRANSPLANTATION Vol. 79, 1482–1489, No. 5, May 15, 2003
Copyright © 2003 by Lippincott Williams & Wilkins, Inc. Printed in U.S.A.
LIVER TRANSPLANTATION FOR HEPATOPULMONARY
SYNDROME: A TEN-YEAR EXPERIENCE IN PARIS, FRANCE
CAMILLE TAILL
´
E,
1
JACQUES CADRANEL,
2
AGN
`
ES BELLOCQ,
2
GABRIEL THABUT,
1
OLIVIER SOUBRANE,
3
FRANC ¸ OIS DURAND,
1
PHILIPPE ICHA
¨
I,
4
CHRISTOPHE DUVOUX,
5
JACQUES BELGHITI,
1
YVON CALMUS,
3
AND
HERV
´
E MAL
1,6
Background. Although the possibility of reversing
hepatopulmonary syndrome (HPS) after liver trans-
plantation is now well established, the proportion of
patients in whom reversibility is observed and the
time to resolution of HPS remain uncertain.
Methods. We analyzed the outcome of all adult pa-
tients with HPS who underwent orthotopic liver
transplantation in all the liver transplant centers in
Paris, during a 10-year period.
Results. Twenty-three adult patients (median age, 47
years; range, 14 – 64) underwent transplantation in
four institutions. Median PaO
2
was 52 (range, 32– 67)
mm Hg and median alveolar-arterial oxygen gradient
was 66 mm Hg. When patients were breathing 100% O
2
,
median PaO
2
was 310 (range, 74 – 663) mm Hg. Median
isotopic shunt ratio was 33% (range, 0 – 80%). The over-
all mortality during the study period was 30.5% (7/23).
Perioperative mortality was 8.5%, whereas late mor-
tality was 22%. None of the preoperative characteris-
tics of HPS (isotopic shunt ratio, PaO
2
on room air or
on 100% oxygen) was associated with overall postop-
erative mortality. Of the 21 patients surviving the
perioperative period (median follow-up, 17 months;
range, 0.5–72), a decrease in alveolar-arterial oxygen
gradient of at least 5 mm Hg and at least 10 mm Hg was
observed in 21 of 21 and in 18 of 21 patients, respec-
tively, with great variations in the time of improve-
ment. The threshold of 70 mm Hg was reached in 15
patients. The lower the preoperative PaO
2
, the longer
the time to reach this point.
Conclusion. Our data strongly support the role of
orthotopic liver transplantation in adult patients with
HPS, regardless of its severity.
Hepatopulmonary syndrome (HPS) is defined as a triad of
liver disease, increased alveolar-arterial oxygen gradient
[P(A-a)O
2
] on room air (RA), and evidence of intrapulmonary
vascular dilatation (1). This complication was initially con-
sidered a contraindication for liver transplantation when
severe debilitating hypoxemia was present because of an
expected increase in early postoperative mortality and un-
certainties concerning long-term outcome. However, several
case reports have subsequently demonstrated that even in
severe cases, hypoxemia could reverse after transplantation.
As a result, most centers currently consider that HPS repre-
sents an indication for liver transplantation per se, whatever
the severity of the underlying liver disease (2). However, data
on the proportion of patients in whom HPS reversibility is
observed and on the resolution delay, especially in patients
with severe preoperative hypoxemia, remain poorly defined.
Moreover, predictors of mortality and reversibility have been
proposed (3) but have not been confirmed. The aim of this
retrospective multicenter study was to address these issues
by analyzing the outcome of all adult patients with HPS who
underwent orthotopic liver transplantation (OLT) in all Pa-
risian transplant centers during a 10-year period, with spe-
cial emphasis on morbidity and mortality of OLT in this
setting, prevalence of reversal of HPS, and time to improve-
ment of gas exchange.
PATIENTS AND METHODS
In December 2000, the medical director of each of the six adult
liver transplantation centers of the “Assistance Publique–Ho ˆpitaux
de Paris,” was contacted to collect all cases of patients with HPS who
underwent OLT from January 1991 to December 2000. Diagnostic of
HPS was established in patients with chronic liver disease present-
ing with PaO
2
less than 70 mm Hg or P(A-a)O
2
more than 20 mm Hg
on RA and with delayed (more than three cardiac cycles) positive
contrast-enhanced echocardiography (4). The medical charts of all
patients who fulfilled the selection criteria were analyzed retrospec-
tively by one of us (C.T.). No patient was excluded from analysis.
Collection of Preoperative HPS Characteristics
We collected preoperative values of arterial blood gases (ABG) at
rest and in a supine position on RA and in response to 100% O
2
.
P(A-a)O
2
was calculated using the measured PaO
2
and PaCO
2
and
alveolar oxygen tension calculated from the alveolar gas equation
assuming a standard respiratory exchange ratio of 0.8. Oximetric
shunt ratio (OSR) was estimated during 100% O
2
breathing and was
based on an assumed arteriovenous oxygen content difference of 5
mL/dL (5).
Isotopic shunt ratio (ISR) was also assessed by
99m
Tc-macroaggre-
gated albumin perfusion lung scan in 19 patients. The amount of
radioactivity was measured over the lungs and, according to the
centers, over kidneys, brain, or the whole body using a scintillation
camera. The ratio of systemic to total body activity (lungs and sys-
temic) is an estimate of the magnitude of the shunt fraction. Shunt
fraction was considered significant if greater than 6%, regardless of
the technique (6). ISR was calculated from the radioactivity mea-
sured over the brain, kidneys, or brain and kidneys in 11, 1, and 7
patients, respectively, assuming that the cerebral and renal circula-
tion receive approximately 13% and 25% of the cardiac output in the
resting state, respectively (6,7).
1
Service de Pneumologie et de R
´
eanimation Respiratoire et IN-
SERM U408, Service d’H
´
epatologie, Service de Chirurgie Digestive,
Ho ˆpital Beaujon, Clichy, France.
2
Service de Pneumologie et de R
´
eanimation Respiratoire, Service
d’Explorations Fonctionnelles, Ho ˆpital Tenon, Paris, France.
3
Service de Chirurgie Digestive, Ho ˆpital Cochin, Paris, France.
4
Centre H
´
epato-Biliaire, Ho ˆpital Paul Brousse, Villejuif, France.
5
Service d’H
´
epatologie, Ho ˆpital Henri Mondor, Cr
´
eteil, France.
6
Address correspondence to: Herv
´
e Mal, M.D., Service de Pneumologie
et de R
´
eanimation Respiratoire, Ho ˆpital Beaujon, 100 avenue du G
´
en
´
eral
Leclerc, 92110, Clichy, France. E-mail: herve.mal@bjn.ap-hop-paris.fr.
Received 14 June 2002.
Revision Requested 17 July 2002. Accepted 8 January 2003.
1482 DOI: 10.1097/01.TP.0000061612.78954.6C