1600
The Journal of Rheumatology 2014; 41:8; doi:3899/jrheum.131449
Personal non-commercial use only. The Journal of Rheumatology Copyright © 2014. All rights reserved.
Effect of Remission Definition on Healthcare Cost
Savings Estimates for Patients with Rheumatoid
Arthritis Treated with Biologic Therapies
Cheryl Barnabe, Nguyen Xuan Thanh, Arto Ohinmaa, Joanne Homik, Susan G. Barr,
Liam Martin, and Walter P. Maksymowych
ABSTRACT. Objective. Sustained remission in rheumatoid arthritis (RA) results in healthcare utilization cost
savings. We evaluated the variation in estimates of savings when different definitions of remission
[2011 American College of Rheumatology/European League Against Rheumatism Boolean
Definition, Simplified Disease Activity Index (SDAI) ≤ 3.3, Clinical Disease Activity Index (CDAI)
≤ 2.8, and Disease Activity Score-28 (DAS28) ≤ 2.6] are applied.
Methods. The annual mean healthcare service utilization costs were estimated from provincial
physician billing claims, outpatient visits, and hospitalizations, with linkage to clinical data from the
Alberta Biologics Pharmacosurveillance Program (ABioPharm). Cost savings in patients who had a
1-year continuous period of remission were compared to those who did not, using 4 definitions of
remission.
Results. In 1086 patients, sustained remission rates were 16.1% for DAS28, 8.8% for Boolean, 5.5%
for CDAI, and 4.2% for SDAI. The estimated mean annual healthcare cost savings per patient
achieving remission (relative to not) were SDAI $1928 (95% CI 592, 3264), DAS28 $1676 (95% CI
987, 2365), and Boolean $1259 (95% CI 417, 2100). The annual savings by CDAI remission per
patient were not significant at $423 (95% CI –1757, 2602). For patients in DAS28, Boolean, and
SDAI remission, savings were seen both in costs directly related to RA and its comorbidities, and in
costs for non-RA-related conditions.
Conclusion. The magnitude of the healthcare cost savings varies according to the remission
definition used in classifying patient disease status. The highest point estimate for cost savings was
observed in patients attaining SDAI remission and the least with the CDAI; confidence intervals for
these estimates do overlap. Future pharmacoeconomic analyses should employ all response defini-
tions in assessing the influence of treatment. (First Release July 15 2014; J Rheumatol 2014;41:
1600–606; doi:10.3899/jrheum131449)
Key Indexing Terms:
RHEUMATOID ARTHRITIS BIOLOGICS HEALTHCARE COSTS
OUTCOME ASSESSMENT REMISSION DEFINITIONS
From the Department of Medicine, University of Calgary, Calgary;
Department of Community Health Sciences, University of Calgary,
Calgary; Institute of Health Economics, Edmonton; School of Public
Health, University of Alberta, Edmonton; and Department of Medicine,
University of Alberta, Edmonton, Alberta, Canada.
The Alberta Biologics Pharmacosurveillance Program (ABioPharm) was
supported by a grant from Alberta Health and Wellness for the study
period reported.
C. Barnabe, MD, MSc, FRCPC, Department of Medicine and Department
of Community Health Sciences, University of Calgary; N.X. Thanh, MD,
PhD, MPH, Institute of Health Economics and School of Public Health,
University of Alberta; A. Ohinmaa, PhD, Institute of Health Economics
and School of Public Health, University of Alberta; J. Homik, MD, MSc,
FRCPC, Department of Medicine, University of Alberta; S.G. Barr, MD,
MSc, FRCPC, Department of Medicine, and Department of Community
Health Sciences, University of Calgary; L. Martin, MB, ChB, FRCPC,
Department of Medicine, University of Calgary; W.P. Maksymowych, MB,
ChB, FRCPC, Department of Medicine, University of Alberta.
Address correspondence to Dr. C. Barnabe, Department of Medicine,
University of Calgary, 3330 Hospital Drive NW, Calgary, Alberta
T2N 4N1. E-mail: ccbarnab@ucalgary.ca
Accepted for publication April 17, 2014.
The cost of biologic therapies to control disease-modifying
antirheumatic drug (DMARD)-refractory rheumatoid
arthritis (RA) has driven the development and refinement of
cost-effectiveness modeling using both clinical trial and
registry data. These analyses incorporate the cost of the new
treatment offset by improvements in work productivity and
future reduced health resource utilization
1
. Cost-effec-
tiveness models are recognized to vary greatly in their
inputs, namely in the assumptions made around patient
disease characteristics, disability progression, treatment
sequences, cycle length, medication dosing and wastage,
risk of adverse effects, disease complications and mortality,
comorbidity, and fluctuations in Health Assessment
Questionnaire (HAQ) scores that are used as a surrogate to
estimate health utility for the estimates
2
.
Another source of variation is in the choice of effec-
tiveness data for the modeling, specifically the use of
Disease Activity Scores (DAS)
3
or American College of
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