S-65
Department of Neurology, Istanbul Faculty
of Medicine, Istanbul University,
Istanbul, Turkey.
Nilüfer Yesilot, MD; Mehdi Shehu, MD;
Oget Oktem-Tanor, PhD; Piraye
Sedaroglu, MD; Gülsen Akman-Demir,
MD.
* These authors contributed equally and-
share first authorship.
Please address correspondence to:
Gulsen Akman-Demir, Istanbul Faculty of
Medicine Department of Neurology, Çapa
34390 Istanbul, Turkey.
E-mail: akmandem@istanbul.edu.tr
Received on April 4, 2005; accepted in
revised form on September 30, 2005.
Clin Exp Rheumatol 2006; 24 (Suppl. 42):
S65-S70.
© Copyright CLINICAL AND EXPERIMEN-
TAL RHEUMATOLOGY 2006.
Key words: Behçet’s disease, neuro-
logical involvement, subclinical
(‘silent’) neurological involvement.
ABSTRACT
Objective. The aim of this study was to
determine the long term clinical course
and prognosis of subclinical (‘silent’)
neurological involvement in Behçet’s
disease (BD).
Methods. We included patients with
BD who did not have any neurological
complaints other than headache, dizi-
ness or other non-specific complaints,
that showed abnormal neurological
findings (Silent Group). We compared
these patients with the patients with
overt parenchymal neuro-Behçet’s dis-
ease (Overt Group). Cases with at least
8 years of follow-up were included.
Results. There were 22 patients in the
Silent Group (15M, 7F), with a mean
follow-up of 12.8 ± 4 years. Magnetic
resonance imaging was abnormal in 8
of 21 patients, while neuropsychologi-
cal testing revealed mild abnormalities
in 15 of 20 patients. During the follow
up period, 3 patients of the Silent
Group had 4 overt neurological at-
tacks. In the last visit, 21 patients were
independent, while one that had previ-
ously developed overt neurological
attack was deceased. The Overt Group
consisted of 51 patients (45M, 6F). In
the Overt Group the ratio of males was
higher, nearing a marginal significance
(p = 0.051); whereas age at onset of
BD, and frequency of other organ man-
ifestations of BD were not different. In
the Overt Group at the final visit, 19
patients were independent (37%),
while the remaining were either depen-
dent to others, or deceased, which was
significantly higher when compared to
the Silent Group (p = 0.005).
Conclusion. Silent neurological in-
volvement in BD seems to represent a
milder form of the disease, since the
mortality and disability rate in this
group is significantly low.
Introduction
Behçet’s disease (BD), first described
in 1937 as a disease characterized by
recurrent uveitis, oral aphts and genital
ulcers (1), is a multisystemic inflam-
matory disorder with unknown etiolo-
gy. It is more common among males,
and this male predominance becomes
further pronounced when there is any
serious organ involvement (2, 3).
Neurological manifestations may occur
in about 5% of BD patients (4), which
is generally confined to central nervous
system (CNS). Mainly two patterns of
CNS involvement may be seen. Par-
enchymal CNS involvement is the
more common form usually involving
brainstem, or occasionally spinal cord.
Although motor and cognitive signs
predominate the clinical picture, brain-
stem signs, sphyncteric dysfunction,
pyramidocerebellar syndrome and sen-
sory findings may also be found (5).
Onset is usually with a subacutely
evolving attack followed by remission
with or without sequelae. After the
attack(s) some of the cases show a slow
progression (secondary progressive
course). In a minority of the cases,
there is an insidious onset without any
clear-cut attack, showing a slow but
continuous progression (primary pro-
gressive course) (5-7). An attack of
parenchymal involvement is usually
accompanied by cerebrospinal fluid
(CSF) pleocytosis, and shows a typical
magnetic resonance imaging (MRI)
finding with a brainstem lesion extend-
ing to diencephalic structures, or to
basal ganglia region (8). The large le-
sion seen during an attack tends to
become smaller or may disappear dur-
ing follow-up (8). Although less fre-
quently, subcortical and periventricular
white matter lesions may also be seen
(9). On the other hand, non-parenchy-
mal CNS involvement mainly repre-
sents CNS findings due to major vascu-
lar involvement. More commonly, in-
creased intracranial pressure is encoun-
tered due to venous sinus thrombosis.
In this setting cranial MRI usually does
not reveal any parenchymal abnormali-
ties, and CSF is usually normal other
than high pressure. Less frequently,
Silent neurological involvement in Behçet’s disease
N. Yesilot*, M. Shehu*, O. Oktem-Tanor, P. Serdaroglu, G.Akman-Demir